Journal article
Angiolymphoid Hyperplasia With Eosinophilia Within a Vascular Malformation: Case Report and Review of the Literature
Annals of otology, rhinology & laryngology, Vol.125(9), pp.775-778
09/2016
DOI: 10.1177/0003489416646796
PMID: 27141028
Abstract
Angiolymphoid hyperplasia with eosinophilia (ALHE) is a rare, benign microvascular proliferation tumor. The etiology of ALHE is unknown, though some hypothesize it occurs in reaction to focal trauma. This study presents a case of AHLE within a vascular malformation, its treatment, and a review of the literature.
A retrospective case report was performed with a 4-year follow-up. Medical records including clinic notes, radiography, operative reports, pathology, and long-term follow-up were reviewed.
Radiologic imaging revealed a vascular malformation with highly tortuous, corkscrew-shaped arterial vessels. Histology revealed midsized vessels with plump, epithelialized endothelium and focal areas of lymphocytic infiltrate punctuated with eosinophils, consistent with ALHE.
This case demonstrates a unique presentation of ALHE in association with vascular malformation. Initial physical exam lacked the classic dermatologic presentation of clusters of red-to-brown nodules; however, the corkscrew vessels lined by epithelized endothelial cells and eosinophilic infiltrate were pathognomonic for ALHE.
Details
- Title: Subtitle
- Angiolymphoid Hyperplasia With Eosinophilia Within a Vascular Malformation: Case Report and Review of the Literature
- Creators
- Stefani C Fontana - University of Kansas School of Medicine, Department of Otolaryngology, Kansas City, Kansas, USAAshley Borgstadt - University of Kansas School of Medicine, Department of Otolaryngology, Kansas City, Kansas, USAGarth R Fraga - University of Kansas School of Medicine, Department of Pathology, Kansas City, Kansas, USAAlan R Reeves - University of Kansas School of Medicine, Department of Radiology, Kansas City, Kansas, USABrian T Andrews - University of Kansas School of Medicine, Department of Otolaryngology, Kansas City, Kansas, USA bandrews@kumc.edu
- Resource Type
- Journal article
- Publication Details
- Annals of otology, rhinology & laryngology, Vol.125(9), pp.775-778
- DOI
- 10.1177/0003489416646796
- PMID
- 27141028
- NLM abbreviation
- Ann Otol Rhinol Laryngol
- ISSN
- 0003-4894
- eISSN
- 1943-572X
- Language
- English
- Date published
- 09/2016
- Academic Unit
- Craniofacial Anomalies Research Center; Neurosurgery; Otolaryngology
- Record Identifier
- 9984107403302771
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