Cystic lymphangiomatosis with severe intra-abdominal bleeding in a newborn: Case report

Didem Baskin; Adnan Narci; Nazan Okur; Meltem Ugras; Gulengul Nadirgil Koken; Ahmet Ali Tuncer; Cigdem Tokyol; Salih Cetinkursun

doi:10.1002/jcu.21956

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Cystic lymphangiomatosis with severe intra-abdominal bleeding in a newborn: Case report

Journal article

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Cystic lymphangiomatosis with severe intra-abdominal bleeding in a newborn: Case report

Didem Baskin, Adnan Narci, Nazan Okur, Meltem Ugras, Gulengul Nadirgil Koken, Ahmet Ali Tuncer, Cigdem Tokyol and Salih Cetinkursun

Journal of clinical ultrasound, Vol.41(4), pp.261-264

05/2013

DOI: 10.1002/jcu.21956

PMID: 22729896

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Abstract

We report the case of a newborn girl with intestinal cystic lymphangiomatosis who presented with abdominal distension and intra-abdominal bleeding following a prenatal ultrasound diagnosis of intestinal anomaly. Postnatal abdominal ultrasound revealed disseminated submucosal and intramural cystic dilatations of various sizes in the bowel and intestinal lymphangiomatosis was diagnosed. The presence of severe bleeding diathesis and widespread disease led to conservative treatment. The patient died on postnatal day 7 and postmortem examination confirmed cystic lymphangiomatosis. Detection of intestinal hyperechogenicity and/or dilatation in prenatal ultrasonography and the persistence of these findings during pregnancy are suggestive for pathologies such as meconium ileus, meconium peritonitis, and intestinal atresia. Although rare, intestinal lymphangiomatosis should be kept in mind in patients whose prenatal sonographic findings persist until birth. (c) 2012 Wiley Periodicals, Inc. J Clin Ultrasound, 2013

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Title: Subtitle: Cystic lymphangiomatosis with severe intra-abdominal bleeding in a newborn: Case report
Creators: Didem Baskin - Afyon Kocatepe Univ, Fac Med, Dept Pediat Surg, Afyon, Turkey
Adnan Narci - Afyon Kocatepe Univ, Fac Med, Dept Pediat Surg, Afyon, Turkey
Nazan Okur - Afyon Kocatepe University
Meltem Ugras - Usak University
Gulengul Nadirgil Koken - Afyon Kocatepe University
Ahmet Ali Tuncer - Afyon Kocatepe University
Cigdem Tokyol - Afyon Kocatepe University
Salih Cetinkursun - Afyon Kocatepe University
Resource Type: Journal article
Publication Details: Journal of clinical ultrasound, Vol.41(4), pp.261-264
DOI: 10.1002/jcu.21956
PMID: 22729896
ISSN: 0091-2751
eISSN: 1097-0096
Publisher: Wiley
Number of pages: 4
Language: English
Date published: 05/2013
Academic Unit: Stead Family Department of Pediatrics; Gastroenterology, Hepatology, Pancreatology, and Nutrition
Record Identifier: 9985214104402771

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