Intraosseous hair-induced cyst-like lesion of the maxilla associated with trichotillomania: first reported case and review of the literature

Jay Saepoo; Steven Dorris; Kittiphoj Tikkhanarak; Sherry Timmons; Nidhi Handoo; John Hellstein; Adam Holton; Emily Lanzel

doi:10.1007/s10006-025-01495-4

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Intraosseous hair-induced cyst-like lesion of the maxilla associated with trichotillomania: first reported case and review of the literature

Journal article

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Intraosseous hair-induced cyst-like lesion of the maxilla associated with trichotillomania: first reported case and review of the literature

Jay Saepoo, Steven Dorris, Kittiphoj Tikkhanarak, Sherry Timmons, Nidhi Handoo, John Hellstein, Adam Holton and Emily Lanzel

Oral and maxillofacial surgery, Vol.30(1), 13

01/07/2026

DOI: 10.1007/s10006-025-01495-4

PMCID: PMC12779652

PMID: 41498824

Appears in UI Libraries Support Open Access

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Abstract

Heterotopic hair in the oral cavity is a rare condition, with possible etiologies including prior skin graft reconstruction, oral and maxillofacial trauma, or, in some clinical context, no identifiable cause. We report a case of a patient with trichotillomania who presented with a persistent sinus track opening between teeth #9 and #10 and a well-defined periradicular lesion in the area. Microscopically, it revealed a partially lined cyst-like entity containing terminal hairs, associated with a foreign body-type giant cell reaction. The patient admitted to a habit of repeatedly pulling and plucking her hair, placing it in her mouth, and occasionally pressing it against the area of concern. To our knowledge, this is the first reported case of an intraosseous hair-induced cyst-like entity with foreign body reaction in the anterior maxilla associated with trichotillomania.

Adult

Female

Hair

Humans

Maxillary Diseases - diagnosis

Maxillary Diseases - etiology

Maxillary Diseases - pathology

Maxillary Diseases - surgery

Trichotillomania - complications

UIOWA OA Agreement

Details

Title: Subtitle: Intraosseous hair-induced cyst-like lesion of the maxilla associated with trichotillomania: first reported case and review of the literature
Creators: Jay Saepoo - University of Iowa
Steven Dorris - University of Iowa
Kittiphoj Tikkhanarak - University of Iowa
Sherry Timmons - University of Iowa
Nidhi Handoo - University of Iowa
John Hellstein - University of Iowa
Adam Holton - University of Iowa
Emily Lanzel - University of Iowa
Resource Type: Journal article
Publication Details: Oral and maxillofacial surgery, Vol.30(1), 13
DOI: 10.1007/s10006-025-01495-4
PMID: 41498824
PMCID: PMC12779652
NLM abbreviation: Oral Maxillofac Surg
ISSN: 1865-1550
eISSN: 1865-1569
Publisher: Springer Nature
Language: English
Date published: 01/07/2026
Academic Unit: Oral Pathology, Radiology and Medicine; Dentistry Administration
Record Identifier: 9985116170302771

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