Journal article
Successful endovascular treatment of superior mesenteric artery-duodenal fistula secondary to Rapunzel syndrome
Radiology case reports, Vol.18(8), pp.2689-2691
08/01/2023
DOI: 10.1016/j.radcr.2023.05.031
PMCID: PMC10238254
PMID: 37273725
Abstract
Rapunzel syndrome is a rare clinical entity in pediatric patients with a history of trichotillomania and trichophagia that has only been mentioned a few times in the literature. It is characterized by abnormal gastric bezoar formation that sometimes extends to the duodenum, jejunum, or colon. Here, we present a case of a 16-year-old previously healthy female patient who had prolonged hospitalization due to complications related to a significant gastric bezoar that led to massive bleeding due to a superior mesenteric artery (SMA)-duodenal fistula successfully treated with stent graft placement. Undiagnosed trichobezoar can lead to rare and unexpected complications, such as SMA-duodenal fistula, with life-threatening hemorrhagic shock. Prompt activation of massive transfusion protocol and endovascular control of the hemorrhage was vital to successfully treating our patient.
Details
- Title: Subtitle
- Successful endovascular treatment of superior mesenteric artery-duodenal fistula secondary to Rapunzel syndrome
- Creators
- Assim Saad Eddin - University of Iowa Hospitals and ClinicsMohammad Amarneh - University of IowaSawyer Goetz - Department of Radiology, Carver College of Medicine, Iowa City, IA, USAFrancesco Donato
- Resource Type
- Journal article
- Publication Details
- Radiology case reports, Vol.18(8), pp.2689-2691
- DOI
- 10.1016/j.radcr.2023.05.031
- PMID
- 37273725
- PMCID
- PMC10238254
- NLM abbreviation
- Radiol Case Rep
- ISSN
- 1930-0433
- eISSN
- 1930-0433
- Language
- English
- Date published
- 08/01/2023
- Academic Unit
- Radiology; Stead Family Department of Pediatrics; Internal Medicine
- Record Identifier
- 9984426855002771
Metrics
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