Journal article
Validation of the Italian version of the Charcot‐Marie‐Tooth disease Pediatric Scale
Journal of the peripheral nervous system, Vol.25(2), pp.138-142
06/2020
DOI: 10.1111/jns.12383
PMID: 32394473
Abstract
The Charcot‐Marie‐Tooth disease Pediatric Scale (CMTPedS) is a Rasch‐built clinical outcome measure of disease severity. It is valid, reliable, and responsive to change for children and adolescents aged 3 to 20 years. The aim of this study was to translate and validate an Italian version of the CMTPedS using a validated framework of transcultural adaptation. The CMTPedS (Italian) was translated and culturally adapted from source into Italian by two experts in CMT with good English language proficiency. The two translations were reviewed by a panel of experts in CMT. The agreed provisional version was back translated into English by a professional translator. The definitive Italian version was developed during a consensus teleconference by the same panel. CMT patients were assessed with the final version of the outcome measure and a subset had a second assessment after 2 weeks to evaluate test‐retest reliability. Seventeen patients with CMT aged 5 to 20 years (eight female) were evaluated with the CMTPedS (Italian), and test‐retest was performed in three patients. The CMTPedS (Italian) showed a high test‐retest reliability. No patient had difficulty in completing the scale. The instructions for the different items were clearly understood by clinicians and therefore the administration of the outcome measure was straight forward and easily understood by the children assessed. The CMTPedS (Italian) will be used for clinical follow‐up and in clinical research studies in the Italian population. The data is fully comparable to that obtained from the English language version.
Details
- Title: Subtitle
- Validation of the Italian version of the Charcot‐Marie‐Tooth disease Pediatric Scale
- Creators
- Riccardo Zuccarino - Neuromuscular Omnicentre (NEMO)‐Fondazione Serena OnlusValeria Prada - Rehabilitation, Ophthalmology, Genetics and Maternal/Child Sciences, University of Genova and IRCCS San MartinoIsabella Moroni - Fondazione IRCCS Istituto Neurologico Carlo BestaEmanuela Pagliano - Fondazione IRCCS Istituto Neurologico Carlo BestaMaria Foscan - Fondazione IRCCS Istituto Neurologico Carlo BestaGiulia Robbiano - Rehabilitation, Ophthalmology, Genetics and Maternal/Child Sciences, University of Genova and IRCCS San MartinoChiara Pisciotta - Fondazione IRCCS Istituto Neurologico Carlo BestaKayla Cornett - University of Sydney School of Health Sciences & Children's Hospital at WestmeadRosemary Shy - University of Iowa Carver College of MedicineAngelo Schenone - Rehabilitation, Ophthalmology, Genetics and Maternal/Child Sciences, University of Genova and IRCCS San MartinoDavide Pareyson - Fondazione IRCCS Istituto Neurologico Carlo BestaMichael Shy - University of Iowa Carver College of MedicineJoshua Burns - University of Sydney School of Health Sciences & Children's Hospital at Westmead
- Resource Type
- Journal article
- Publication Details
- Journal of the peripheral nervous system, Vol.25(2), pp.138-142
- DOI
- 10.1111/jns.12383
- PMID
- 32394473
- NLM abbreviation
- J Peripher Nerv Syst
- ISSN
- 1085-9489
- eISSN
- 1529-8027
- Publisher
- Wiley Periodicals, Inc; Malden, USA
- Number of pages
- 5
- Grant note
- National Institute of Neurological Disorders and Stroke (R21TR003034) Foundation for the National Institutes of Health (U54NS065712)
- Language
- English
- Date published
- 06/2020
- Academic Unit
- Neurology; Molecular Physiology and Biophysics; Stead Family Department of Pediatrics; Iowa Neuroscience Institute
- Record Identifier
- 9984070162902771
Metrics
21 Record Views